Abstract
Inherited disorders of pulmonary surfactant-associated proteins are rare but provide important insights into unique mechanisms of surfactant dysfunction. Recessive loss-of-function mutations in the surfactant protein-B and the ATP-binding cassette family member A3 (ABCA3) genes present as lethal surfactant deficiency in the newborn, whereas other recessive mutations in ABCA3 and dominant mutations in the surfactant protein-C gene result in interstitial lung disease in older infants and children. The molecular basis and the genetic and tissue-based approaches to the evaluation of children suspected of having one of these disorders are discussed.
Original language | English (US) |
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Pages (from-to) | 311-317 |
Number of pages | 7 |
Journal | Neonatology |
Volume | 91 |
Issue number | 4 |
DOIs | |
State | Published - Jun 2007 |
Keywords
- Genetics
- Lung transplantation
- Newborn
- Pulmonary surfactant
- Respiratory distress syndrome
ASJC Scopus subject areas
- Pediatrics, Perinatology, and Child Health
- Developmental Biology