Spontaneous pneumothorax in cystic adenomatoid malformation: Unusual clinical and histologic features

L. Benture, G. Canny, P. Thorner, R. Superina, P. Babyn, H. Levison*

*Corresponding author for this work

Research output: Contribution to journalArticle

27 Citations (Scopus)

Abstract

Pneumothorax is a rare presentation of congenital cystic adenomatoid malformation (CCAM) in the newborn period and is presumed to be due to resuscitative measures. A previously well three-week-old baby presented with spontaneous tension pneumothorax due to CCAM. In the lung resection specimen, a malformation was seen, which in addition to the histologic changes of CCAM, showed diffuse vascular proliferation in the interstitium and lining of air space by type 2 pneumocytes. We propose that this is a new variant of CCAM rather than one of the classic three types. The unusual clinical manifestation may be related to the unusual histologic features.

Original languageEnglish (US)
Pages (from-to)1292-1293
Number of pages2
JournalChest
Volume99
Issue number5
StatePublished - Jan 1 1991

Fingerprint

Congenital Cystic Adenomatoid Malformation of Lung
Pneumothorax
Alveolar Epithelial Cells
Blood Vessels
Air
Lung

ASJC Scopus subject areas

  • Pulmonary and Respiratory Medicine
  • Critical Care and Intensive Care Medicine
  • Cardiology and Cardiovascular Medicine

Cite this

Benture, L., Canny, G., Thorner, P., Superina, R., Babyn, P., & Levison, H. (1991). Spontaneous pneumothorax in cystic adenomatoid malformation: Unusual clinical and histologic features. Chest, 99(5), 1292-1293.
Benture, L. ; Canny, G. ; Thorner, P. ; Superina, R. ; Babyn, P. ; Levison, H. / Spontaneous pneumothorax in cystic adenomatoid malformation : Unusual clinical and histologic features. In: Chest. 1991 ; Vol. 99, No. 5. pp. 1292-1293.
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Benture, L, Canny, G, Thorner, P, Superina, R, Babyn, P & Levison, H 1991, 'Spontaneous pneumothorax in cystic adenomatoid malformation: Unusual clinical and histologic features', Chest, vol. 99, no. 5, pp. 1292-1293.

Spontaneous pneumothorax in cystic adenomatoid malformation : Unusual clinical and histologic features. / Benture, L.; Canny, G.; Thorner, P.; Superina, R.; Babyn, P.; Levison, H.

In: Chest, Vol. 99, No. 5, 01.01.1991, p. 1292-1293.

Research output: Contribution to journalArticle

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Benture L, Canny G, Thorner P, Superina R, Babyn P, Levison H. Spontaneous pneumothorax in cystic adenomatoid malformation: Unusual clinical and histologic features. Chest. 1991 Jan 1;99(5):1292-1293.