Abstract
Retinal venous occlusive events are a rare complication of arteriovenous malformations of the retina found in Wyburn-Mason syndrome. The authors present a case of a 28-year-old man diagnosed with Wyburn-Mason syndrome and cutaneous reactive angiomatosis, a reactive angioproliferative disorder induced by vascular occlusion. He developed a central retinal vein occlusion complicated by macular edema and received treatment with intravitreal bevacizumab, which led to resolution of the edema. To the best of the authors' knowledge, this is the first report of an anti-vascular endothelial growth factor agent employed as an effective treatment for macular edema in the setting of Wyburn-Mason syndrome. The association between Wyburn-Mason syndrome and cutaneous reactive angiomatosis is also a novel finding.
| Original language | English (US) |
|---|---|
| Pages (from-to) | 760-762 |
| Number of pages | 3 |
| Journal | Ophthalmic Surgery Lasers and Imaging Retina |
| Volume | 46 |
| Issue number | 7 |
| DOIs | |
| State | Published - Jul 1 2015 |
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ASJC Scopus subject areas
- Surgery
- Ophthalmology
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Wyburn-Mason Syndrome Associated with Cutaneous Reactive Angiomatosis and Central Retinal Vein Occlusion. / Callahan, Alison B.; Skondra, Dimitra; Krzystolik, Magdalena; Yonekawa, Yoshihiro; Eliott, Dean.
In: Ophthalmic Surgery Lasers and Imaging Retina, Vol. 46, No. 7, 01.07.2015, p. 760-762.Research output: Contribution to journal › Article
TY - JOUR
T1 - Wyburn-Mason Syndrome Associated with Cutaneous Reactive Angiomatosis and Central Retinal Vein Occlusion
AU - Callahan, Alison B.
AU - Skondra, Dimitra
AU - Krzystolik, Magdalena
AU - Yonekawa, Yoshihiro
AU - Eliott, Dean
PY - 2015/7/1
Y1 - 2015/7/1
N2 - Retinal venous occlusive events are a rare complication of arteriovenous malformations of the retina found in Wyburn-Mason syndrome. The authors present a case of a 28-year-old man diagnosed with Wyburn-Mason syndrome and cutaneous reactive angiomatosis, a reactive angioproliferative disorder induced by vascular occlusion. He developed a central retinal vein occlusion complicated by macular edema and received treatment with intravitreal bevacizumab, which led to resolution of the edema. To the best of the authors' knowledge, this is the first report of an anti-vascular endothelial growth factor agent employed as an effective treatment for macular edema in the setting of Wyburn-Mason syndrome. The association between Wyburn-Mason syndrome and cutaneous reactive angiomatosis is also a novel finding.
AB - Retinal venous occlusive events are a rare complication of arteriovenous malformations of the retina found in Wyburn-Mason syndrome. The authors present a case of a 28-year-old man diagnosed with Wyburn-Mason syndrome and cutaneous reactive angiomatosis, a reactive angioproliferative disorder induced by vascular occlusion. He developed a central retinal vein occlusion complicated by macular edema and received treatment with intravitreal bevacizumab, which led to resolution of the edema. To the best of the authors' knowledge, this is the first report of an anti-vascular endothelial growth factor agent employed as an effective treatment for macular edema in the setting of Wyburn-Mason syndrome. The association between Wyburn-Mason syndrome and cutaneous reactive angiomatosis is also a novel finding.
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UR - http://www.scopus.com/inward/citedby.url?scp=84939435775&partnerID=8YFLogxK
U2 - 10.3928/23258160-20150730-12
DO - 10.3928/23258160-20150730-12
M3 - Article
C2 - 26247458
AN - SCOPUS:84939435775
VL - 46
SP - 760
EP - 762
JO - Ophthalmic Surgery Lasers and Imaging Retina
JF - Ophthalmic Surgery Lasers and Imaging Retina
SN - 2325-8160
IS - 7
ER -